Journal of Family Medicine and Primary Care

CASE REPORT
Year
: 2019  |  Volume : 8  |  Issue : 3  |  Page : 1284--1286

Congenital dilatation of the nasolacrimal sac (Dacryocystocele): Case report


Sakiyeva Kanshaiym1, Mohamed H. Naser El-Din2, Ibrahim A Abdelazim3, Mohamed E S. Hamed2, Tatyana Starchenko1,  
1 Department of Obstetrics and Gynecology №1, Marat Ospanov, West Kazakhstan State Medical University, Aktobe, Kazakhstan
2 Ain Shams University, Cairo, Egypt
3 Ain Shams University, Cairo, Egypt; Ahmadi Hospital, Kuwait Oil Company, Ahmadi, Kuwait

Correspondence Address:
Prof. Ibrahim A Abdelazim
Department of Obstetrics and Gynecology, Ain Shams University, Cairo, Egypt and Ahmadi Kuwait Oil (KOC) Company Hospital, Ahmadi

Abstract

Congenital dacryocystoceles are usually diagnosed in the third trimester by parental ultrasound as a cystic lesion adjacent to the medial and inferior aspects of the fetal orbit. A considerable number of dacryocystocele are bilateral and resolve spontaneously in utero and/or immediately after delivery. Persistent dacryocystoceles need ophthalmological consultation to avoid the possible potential complications. This case report represents a case of congenital dacryocystocele diagnosed by antenatal 2D and 3D ultrasounds, which disappeared spontaneously 2 days after birth. To highlight that, the diagnosis of congenital dacryocystoceles is important to avoid additional postnatal diagnostic techniques and to manage the potential postnatal complications.



How to cite this article:
Kanshaiym S, El-Din MH, Abdelazim IA, Hamed ME, Starchenko T. Congenital dilatation of the nasolacrimal sac (Dacryocystocele): Case report.J Family Med Prim Care 2019;8:1284-1286


How to cite this URL:
Kanshaiym S, El-Din MH, Abdelazim IA, Hamed ME, Starchenko T. Congenital dilatation of the nasolacrimal sac (Dacryocystocele): Case report. J Family Med Prim Care [serial online] 2019 [cited 2019 Jul 18 ];8:1284-1286
Available from: http://www.jfmpc.com/text.asp?2019/8/3/1284/254858


Full Text



 Introduction



Congenital dacryocystoceles are usually diagnosed in the third trimester by parental ultrasound as a cystic lesion adjacent to the medial and inferior aspects of the fetal orbit.[1]

A considerable number of dacryocystocele are bilateral and resolve spontaneously in utero and/or immediately after delivery.[1],[2]

Persistent dacryocystoceles need ophthalmological consultation to avoid the possible potential complications.[2]

 Case Report



A 38-year old, 34-week pregnant female was diagnosed with fetal right-sided cystic lesion adjacent to the medial and inferior aspects of the fetal orbit (dacryocystocele) [Figure 1].{Figure 1}

The 2D ultrasound diagnosis of dacryocystocele was confirmed by the 3D ultrasound scan [Figure 2] and at birth by a bluish cystic swelling below the medial canthal area [Figure 3].{Figure 2}{Figure 3}

The dacryocystocele of the studied case disappeared spontaneously 2 days after birth.

 Discussion



Dacryocystocele usually resolves spontaneously before birth in 50% of cases. Bilateral dacryocystocele may have intranasal extension and may cause respiratory distress.[1],[2]

Persistent epiphora, conjunctivitis, cellulitis and airway obstruction can occur in cases of persistent dacryocystoceles (bilateral cases).[2]

The 3D ultrasound is helpful to confirm the diagnosis of dacryocystoceles and to avoid additional postnatal diagnostic techniques.[2]

Rogister et al. reported three newborns with dacryocystoceles, one of them developed respiratory distress (bilateral dacryocystoceles) and was managed by marsupialization.[3]

Durmaz et al. reported a case of congenital bilateral dacryocystoceles with intranasal extension in a 3-day old newborn presented with respiratory distress and managed by endoscopic marsupialization.[4] Yin et al. reported a successful management of bilateral dacryocystoceles in a 5-day old girl.[5]

Bachelard-Serra et al. reported three cases of congenital bilateral dacryocystocele diagnosed prenatally by an ultrasound. Two of them developed respiratory distress and were managed by marsupialization.[6]

An initial conservative management of congenital dacryocystocele may be considered, but the surgical management is recommended if there is persistent respiratory obstruction.[7] Sarbajna et al. reported that the endoscopic marsupialization is an effective surgical management for congenital dacryocystocele.[8]

This case report represents a case of congenital dacryocystocele diagnosed by antenatal 2D and 3D ultrasounds, which disappeared spontaneously 2 days after birth. To highlight that, the diagnosis of congenital dacryocystoceles is important to avoid additional postnatal diagnostic techniques and to manage the potential postnatal complications.

 Conclusion



Diagnosis of congenital dacryocystoceles is important to avoid additional postnatal diagnostic techniques and to manage the potential postnatal complications.

Declaration of patient consent

The authors certify that they have obtained all appropriate patient consent forms. In the form the patient has given her consent for her and her child images and other clinical information to be reported in the journal. The patients understand that her and her child names and initials will not be published and due efforts will be made to conceal her and her child identities, but anonymity cannot be guaranteed.

Acknowledgements

The authors are grateful to the studied woman and for her agreement and consent to participate in this case report (signed consent taken from the studied woman).

Financial support and sponsorship

The case report was funded by the authors themselves.

Conflicts of interest

There are no conflicts of interest.

References

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